Document pev934QE8m3eGbXEX2XOvB7Kw
Myeloma
Protein
Kinetics
Following
Chemotherapy
By Peter McLaughlin and Raymond Alexanian
The effects of chemotherapy
were evaluated
in 43 multiple
myeloma
patients
with high monoclonal
globulin levels in
both serum and urine. In responding
patients. Bence Jones
protein excretion
declined more rapidly and markedly than
the serum myeloma protein. Bence Jones protein excretion
was reduced by 50% within 2 mo in responders.
remained
unchanged
in nonresponders.
and declined
with a slow
halving time of 2-7 mo in patients
with partial disease
I N MOST
PATIENTS
with multiple myeloma,
changes in serum myeloma protein production rate
have provided the best available index of tumor mass
change from chemotherapy.'2
The utility of systematic
Bence Jones protein (BJP) quantitations
in defining
remission and relapse has been less clear, primarily
because the relation of changing
BJP excretion
to
variations in tumor mass has not been defined. Thus,
the significance
of a specific reduction in BJP excre-
tion following chemotherapy
is unknown. Such knowl-
edge would also provide a more realistic appraisal of
remission and relapse in the 20% of myeloma patients
with light chain excretion as their only protein abnor-
mality.
This study evaluated serum myeloma proteins and
Bence Jones protein excretion
simultaneously
in a
large number of patients receiving chemotherapy.
Results indicated that a rapid and marked decline of
BJP excretion provided the earliest evidence that a
remission
would develop, sometimes
months before
definitive changes in the serum myeloma protein had
occurred. With rare exceptions,
the eventual magni-
tude of tumor reduction was predicted from the rate of
BJP decline during the first 2 mo of treatment.
MATERIALS
AND METHODS
The records of 525 consecutive, previously untreated patients with
multiple myeloma referred to the University of Texas M.D. Ander-
son Hospital between September
1965 and December
1980 were
reviewed. Only patients with both serum myeloma protein exceeding
2.0 g/dl and BJP excretion greater than I .0 g/day were eligible for
study. Only those patients with at least 4 myeloma protein measure-
ments in both serum and urine for at least 6 mo following the start of
chemotherapy
were analyzed. Patients with renal abnormalities
(i.e.,
BUN >40 mg/dl or 24-hr urinary albumin > I g) were analyzed
separately. Among patients with marked albuminuria,
those with a
urine monoclonal component of the same electrophoretic
mobility as
the serum myeloma protein were excluded because light chain
excretion could not be quantitated.
All patients received intermittent
courses of an alkylating agent with prednisone, many also receiving
vincristine and doxorubicin
in accordance with specific protocols.3
Changes in the serum myeloma globulin concentration
were
measured from the electrophoretic
strip in patients with IgG and
high lgA peaks, and from the direct immunoglobulin
quantitation
in
patients with IgA monoclonal globulins falling to less than 2.0 g/dl.
control.
Three patients
with clinical resistance
to treat-
ment showed atypical protein changes and progressively
more Bence Jones protein excretion
relative to their serum
monoclonal
component.
Serial measurements
of Bence
Jones protein excretion
provided
an early and reliable
index of tumor mass change in patients
with multiple
myeloma.
Variations in myeloma tumor mass were calculated from changes in
serum myeloma protein production rate using techniques described
previously. .2 BJ P excretion/day
was determined
simultaneously
from the product of the 24-hr urine protein excretion and the percent
light chain globulin on urine electrophoresis.
Patients were classified into three response groups depending on
the magnitude of reduction in serum myeloma protein production as
an index of tumor mass change, as described previously.'2
Respond-
ers eventually reduced serum myeloma proteins by at least 75%,
"improved"
patients by 50%-74%, and nonresponders
showed less
than a 50% reduction. The response of three atypical patients was
difficult to classify and these patients were analyzed separately.
Survival was calculated from life-table calculations
with statistical
comparisons by the Wilcoxon technique.
RESULTS
Because of the specific pretreatment
and serial
myeloma protein measurements
required, the analysis
was limited to those 43 patients who had complete data
for at least 6 mo. The clinical features of these patients
are summarized
in Table 1 . In these selected patients
with high monoclonal globulin levels in both serum and
urine, the median serum peak was 4.7 g/dl and the
median BJP was 2.1 g/day. Since the kinetics of serum
myeloma protein and BJP change in the I 2 patients
with renal disease were similar to those without renal
abnormalities
for each response
category,
these
patients were included in the analysis.
In each patient, the percentage
change in BJP
excretion following chemotherapy
was compared with
the percentage
decline in serum myeloma
protein
production
as the primary index of tumor mass
change.' As indicated in Fig. I, 16 of 20 responding
patients reduced serum myeloma
protein by 50%
within 2 mo, the serum peak disappearing
from the
electrophoretic
strip in 4 of these patients. All respond-
ing patients showed a rapid reduction of BJP excretion
From the University
of Texas M.D. Anderson
Hospital
and
Tumor Institute, Houston, Texas.
Submitted
July /3, 198/: accepted May 20, 1982.
Address reprint requests to Peter McLaughlin.
M.D. . Depart-
ment of Medicine. M.D. Anderson Hospital and Tumor Institute.
6723 Bertner Avenue, Houston, Texas 77030.
1982 by Grune & Stratton, Inc.
0006-497//82/6005--0008$O/
.00/0
Blood, Vol. 60, No. 4 (October), 1982
851
852
Table 1 . Clinical Features of Patients
No. of patients Medianage No. Hb <8.5 g/dl No. calcium > 1 1 .5 mg/dl No. BUN >40 mg/dl No. high tumor mass Median survival (mo) Myeloma proteins
No.lgGpeak Median g/dl
No.lgApeak Median g/dl
Median BJP excretion (g/day)
#{149}Thr patients with atypical
Responsive
20 57
4 2 3 8 48
14 4.8 6 4.7 2.0
Improved
9 60
2
1
1 4 23
7 4.6 2 6.4 2.5
changes were excluded.
Unresponsive
11 55
1 0 1 5 12
6 5.6 5 4.4 2.2
by at least 50% within 2 mo and by 90% to less than 200 mg/day within 4 mo. Among 4 patients with very slow declines in serum myeloma protein (i.e., halving time 4-8 mo), all showed a more rapid decline of BJP
RESPONDERS
McLAUGHLIN AND ALEXANIAN
excretion, with a halving time of 0.5-2 mo; the serum
peak concentration
had declined by only 1 59o-3O% by
the time that BJP excretion had been reduced by more
than 50%.
Unresponsive
patients showed a different pattern of
myeloma protein change (Fig. 1). None of the 1 1
unresponsive
patients reduced either the serum my-
eloma proteins or BJP excretion
by 50%, a clear
plateau in BJP excretion being evident in all within 4
mo of treatment.
In "improved"
patients, myeloma proteins fell in a
pattern intermediate
to that found in responsive and
unresponsive
patients (Fig. 2). All reduced their serum
myeloma protein by 50%-74% and their BJP by more
than 50%, but BJP excretion declined slowly with a
median halving time of 4 mo (range 2-7 mo). BJP
disappeared
eventually
in 2 "improved"
patients but
persisted at more than 250 mg/day in the remaining 7
(Fig. 2).
The median survival times for responders,
improved
patients, and nonresponders
were 48, 23, and 12 mo,
RESPONDERS
a,
>
C
a, E
Ca a, a,
0.
0
C
0
C)
V 0 0.
C
a,
0
0.
Ca NON-RESPONDERS E
0
a,
(I)
a,
g
100
NON-RESPONDERS
E
I-
a, Cl)
50
1 2 34 5 5 1
50 0 1 234 567
Months Of Treatment
Fig. 1 . Upper panels indicate responders, showing the slower fall in serum myeloma protein (left) compared to the rapid decline and
disappearance
of urine Bence Jones protein (right). Lower panels show absence of change in unresponsive patients.
CHEMOTHERAPY
AND MYELOMA PROTEIN KINETICS
100%
C
0
a,. .a,
50%
I->
a,-
.E
a,, 0
I-,
a,.,-
>.
Tumor Mass
Improved Patients
100% 50%
20%
UrIne Bence Jones Protein
853
Fig. 2. `improved" urine BJP (right).
10 15
5
Months Of Treatment
patients showed less marked reductions of tumor mass to 25%-50% of control (left) with slow reductions of
respectively.
The survival for responders
was signifi-
cantly better than that for the combined
group of
nonresponders
and improved
patients
(p < 0.01).
Insufficient
patients were available to define whether
responders with very rapid reduction of myeloma pro-
teins lived longer than slow responders.
The rate of BJP reduction was compared among the
three different response groups whose tumor mass
response had been defined from the serum myeloma
protein data. Figure 3 shows clear separations
in the
rate of BJP decline for each response category that
were obvious within several months of treatment.
Three patients showed atypical protein changes.
One responder
had an unusually
slow fall of BJP,
which paralleled a very slow, but eventually marked,
fall of the serum IgA component
(Fig. 4C). One
patient had an initial reduction of the serum IgG peak
by 50%, with a rapid reduction of BJP to 200 mg/day
within 2 wk (Fig. 4A); early clinical relapse with
enlarging subcutaneous
and pleural tumors were then
associated with rapid elevations of both protein compo-
nents. Both of these patients were atypical only in the
speed of their protein changes. One other atypical
patient had persistent urinary BJP despite a decline in
the IgG peak by 75% (Fig. 4B). In this patient, only the
persistent BJP identified him as a nonresponder.
These
patients had most clinical features similar to those of
the other patients. However, two were hypercalcemic
with a high tumor mass, and the serum peak was less
than 3.2 g/dl in all, in comparison
with the median of
4.8 g/dl for all other patients.
The kinetics of protein reduction were also evalu-
ated in 35 consecutive patients who produced only BJP
that had disappeared
following identical chemother-
apy programs. The clinical features of myeloma had
resolved and the patients were considered in remission.
As in responding
patients with serum myeloma pro-
teins, the BJP halving time was less than 2 mo in all.
However, more than 4 mo of treatment was required in
10 patients before BJP disappeared
from the urine,
and all had very high pretreatment
excretion levels
(median 10 g/day). In one patient with 26 g/day of
lambda light chain excretion, disappearance
of BJP
excretion occurred only after 1 8 mo of treatment.
DISCUSSION
While a reduction in serum myeloma protein has
been an accepted
measure
of the total tumor
response,"2
the significance
of a specific decline in
Bence Jones protein excretion
(BJP) has been less
clear. The role of BJP was evaluated
from serial
assessments
of both serum and urine protein markers
in a large number of patients with both abnormalities
who received a standard program of chemotherapy.
Changes in Bence Jones protein excretion provided the
earliest index of either a marked plasma cell reduction
854
100
ci
-
2
0> (I) C 04) 1)
CE
a,
0
Ca
5#{149}..
04)0
C
McLAUGHLIN AND ALEXANIAN
10
I 2 3 4 56
Months Of Treatment
Fig. 3. Degree of BJP decline serum myeloma protein reduction. several months.
as a percent of the pretreatment
value in the three response categories defined from the degree of
A rapid reduction occurred only in responding patients. while nonresponders
were recognized within
or a resistance to chemotherapy.
Thus, BJP excretion
was reduced rapidly and disappeared
in responding
patients,
but persisted
at more than 50% of the
pretreatment
value in all nonresponders,
differences
that were obvious within several months of treatment.
Patients with an intermediate
tumor reduction showed
slower and usually less complete reduction of Bence
Jones protein than achieved
in responders.
BJP
changes correlated
well with other accepted criteria of
remission, even in the presence of renal failure and/or
nephrosis,
and patients responding
by this criterion
had longer survival times. The failure to reduce BJP by
50% within 4 mo after the start of chemotherapy
identified patients with therapeutic
resistance in whom
different treatments
should be instituted early, espe-
cially when advanced disease is present and the prog-
nosis is poor.4 Each of the infrequent exceptions to this
pattern appeared to be clinically resistant to chemo-
therapy and showed progressively
less heavy chain and
more light chain production
per cell in the manner
described by Hobbs.5'6 More frequent measurements
of
Bence Jones protein excretion, such as weekly after the
start of chemotherapy,
might have confirmed response
and resistance
trends even earlier in some patients.
Such data could also clarify the important question of
whether the speed of protein reduction has any correla-
tion with prognosis.
The rapid metabolism
of Bence Jones protein proba-
bly accounts for its prompt elimination
from the urine
following a marked reduction
of the myeloma
cell
population.
The half-life for heavy chain immuno-
globulins ranges from 6 days for IgA to 23 days for
IgG components,
and their catabolism
is largely inde-
pendent of the kidney.7 In contrast, the half-life of
Bence Jones protein is less than I day, and the kidney is
the major site of catabolism.8'9
Since the capacity for
CHEMOTHERAP'
AND MYELOMA PROTEIN KINETICS
855
THREE ATYPICAL PATIENTS
a,
.2a,
>
C
aa,
a,
a,
a.
0
C
.2
.
1::N\ a, a, 0 C a, 0
a.
a,
E
>,0
a,
-I,///,////,/,//
10 O 3'O
Months Of Treatment
4O
Fig. 4. Lower panel indicates an atypical patient with slow
declines and eventual disappearance of both urine BJP (dotted
line) and IgA myeloma protein (solid line). With relapse. only BJP
excretion increased markedly. Upper right panel shows a patient
with a marked reduction
of serum myeloma protein but little
change in urine BJP (dotted line). Upper left panel indicates an
atypical patient with a temporary fall in urine BJP (dotted line) that
was followed by early progression of both protein markers and of
multiple tumor masses.
renal catabolism
may exceed 30 g/day in some mye-
loma patients with high production
levels, the urinary
excretion of Bence Jones protein presumably
repre-
sents the excess production
that escapes renal catabo-
lism. Thus, the disappearance
of urinary BJP reflects a
less marked decline of total BJP production and of the
myeloma cell mass than does a comparable
decline in
serum myeloma protein production.
In patients with Bence Jones protein excretion as
their only abnormality,
precise criteria for remission
have been difficult to define. Some centers have
defined remission as a 50% reduction in BJP excretion,
while others have required disappearance.
No studies
have considered the rates of protein change or the time
to disappearance
as a factor. Our studies indicated that
only patients with a rapid rate of BJP reduction
"responded"
in terms of a 75% reduction of serum
myeloma
protein
production.
Because some patients
may have a very high basal BJP excretion, especially
when Bence Jones protein constitutes
the only abnor-
mality, the eventual disappearance
of BJP may require
many months of chemotherapy.
Those patients with
slow reductions
should be considered
resistant
to
chemotherapy
and should be offered promising
new
agents, especially if they are symptomatic.
Some of our patients had atypical BJP changes
following chemotherapy the serum monoclonal
despite a marked decline of
component.
Later BJP eleva-
tions with disease progressionwere
sometimes
than the increments
in the abnormal serum
greater protein.
These patterns were similar to those of Hobbs, who proposed the concept of "Bence Jones escape" to
indicate the emergence of a more primitive plasma cell
subclone with less ability to produce or assemble intact
immunoglobulins.5'6
Presumably
even more dedifferen-
tiation occurred in those uncommon relapsing patients
whose disease progressed with only bone destruction
and/or soft tissue tumors,
of the original myeloma
described several patients
but without any protein. Suchman
with an aggressive
recurrence et al. have
terminal
phase of multiple myeloma with less differentiated
plasma cells.'#{176S}uch atypical relapse patterns empha-
size the importance
of monitoring
serial changes of
myeloma
proteins,
bone lesions, and bone marrow
plasmacytosis
throughout
a patient's course, since
changes in any of these features may herald disease
progression.
ACKNOWLEDGMENT
The authors are indebted to Kay Delasalle, who assisted with the analyses.
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1973
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